{"@context":{"@vocab":"https://cir.nii.ac.jp/schema/1.0/","rdfs":"http://www.w3.org/2000/01/rdf-schema#","dc":"http://purl.org/dc/elements/1.1/","dcterms":"http://purl.org/dc/terms/","foaf":"http://xmlns.com/foaf/0.1/","prism":"http://prismstandard.org/namespaces/basic/2.0/","cinii":"http://ci.nii.ac.jp/ns/1.0/","datacite":"https://schema.datacite.org/meta/kernel-4/","ndl":"http://ndl.go.jp/dcndl/terms/","jpcoar":"https://github.com/JPCOAR/schema/blob/master/2.0/"},"@id":"https://cir.nii.ac.jp/crid/1390282679770428928.json","@type":"Article","productIdentifier":[{"identifier":{"@type":"DOI","@value":"10.2957/kanzo.56.356"}},{"identifier":{"@type":"NDL_BIB_ID","@value":"026614598"}},{"identifier":{"@type":"URI","@value":"http://id.ndl.go.jp/bib/026614598"}},{"identifier":{"@type":"URI","@value":"https://ndlsearch.ndl.go.jp/books/R000000004-I026614598"}},{"identifier":{"@type":"URI","@value":"https://www.jstage.jst.go.jp/article/kanzo/56/7/56_356/_pdf"}},{"identifier":{"@type":"NAID","@value":"130005090873"}},{"identifier":{"@type":"URI","@value":"https://search.jamas.or.jp/link/ui/2016014131"}}],"dc:title":[{"@language":"ja","@value":"Recombinant interleukin-2を投与し6年間経過観察している肺転移を伴う肝類上皮血管内皮腫の1例"},{"@language":"en","@value":"A long-term survival case of hepatic epithelioid hemangioendothelioma with lung metastases treated with recombinant interleukin-2"},{"@value":"症例報告 Recombinant interleukin-2を投与し6年間経過観察している肺転移を伴う肝類上皮血管内皮腫の1例"},{"@language":"ja-Kana","@value":"ショウレイ ホウコク Recombinant interleukin-2 オ トウヨ シ 6ネンカン ケイカ カンサツ シテ イル ハイ テンイ オ トモナウ カンルイ ジョウヒ ケッカン ナイヒ シュ ノ 1レイ"}],"dc:language":"ja","description":[{"type":"abstract","notation":[{"@language":"en","@value":"A 37-year-old woman was found in a medical checkup to have liver dysfunction. Abdominal CT scan images demonstrated multiple liver tumors. She was referred to our hospital for examination and treatment. Abdominal enhanced CT scan images showed irregularly spreading hypovascular tumors located in the surface of both hepatic lobes. Needle liver biopsy revealed many atypical cells with positive staining for factor VIII-related-antigen and CD34. The tumor was diagnosed as an hepatic epithelioid hemangioendothelioma (HEHE). She has received intravenous administration of recombinant interleukin-2 (rIL-2) for six years with a reduction in tumor volume. HEHE is a rare tumor which has low malignant potential, also is often unresectable due to multifocal tumors involving both hepatic lobes at the time of diagnosis. There was no generally accepted therapy except surgical resection and liver transplantation. The long-term survival observed in the present case may indicate the effectiveness of rIL-2 for HEHE."},{"@language":"ja","@value":"症例は37歳女性．2009年1月，健診で肝機能障害を指摘され近医を受診し，単純CTにて肝および肺に多発結節病変を認められたため精査加療目的に当科紹介となった．造影CTでは肝被膜下を中心に境界明瞭な低吸収域が多発し癒合している所見を肝両葉に認めた．肝生検で豊富な硝子様の線維性間質内に腫瘍細胞を認め，免疫染色にて第VIII因子関連抗原，CD34陽性であり肝原発の類上皮血管内皮腫（hepatic epithelioid hemangioendothelioma：HEHE）と診断した．同年4月よりrecombinant interleukin-2（rIL-2）の投与を開始し，6年間外来通院にて治療を継続し，病変体積の減少が得られている．HEHEの生物学的悪性度は低いとされるが，既に腫瘍が肝全体を占めるように多発した切除不能例として発見されることが多い．本疾患の長期間の臨床経過を示した報告が少ないことから，本症例について報告する．"}],"abstractLicenseFlag":"disallow"}],"creator":[{"@id":"https://cir.nii.ac.jp/crid/1410282679770428939","@type":"Researcher","personIdentifier":[{"@type":"NRID","@value":"9000300215425"}],"foaf:name":[{"@language":"ja","@value":"宮西 浩嗣"},{"@language":"en","@value":"Miyanishi Koji"}],"jpcoar:affiliationName":[{"@language":"en","@value":"Department of Medical Oncology and Hematology, Sapporo Medical University School of 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