Intensity of factor VIII treatment and inhibitor development in children with severe hemophilia A: the RODIN study

  • Samantha C. Gouw
    Department of Paediatrics, Wilhelmina Children’s Hospital, University Medical Center Utrecht, Utrecht, The Netherlands;
  • H. Marijke van den Berg
    Julius Center for Health Sciences and Primary Care, University Medical Center Utrecht, Utrecht, The Netherlands;
  • Kathelijn Fischer
    Julius Center for Health Sciences and Primary Care, University Medical Center Utrecht, Utrecht, The Netherlands;
  • Günter Auerswald
    Gesundheit Nord, Klinikum Bremen Mitte, Prof.-Hess-Kinderklinik, Bremen, Germany;
  • Manuel Carcao
    Division of Haematology/Oncology, Hospital for Sick Children, Toronto, Canada;
  • Elizabeth Chalmers
    Department of Haematology, Royal Hospital for Sick Children, Yorkhill, Glasgow, UK;
  • Hervé Chambost
    Service d’hématologie pédiatrique, Hôpital La Timone & Aix-Marseille Univ, Marseille, France;
  • Karin Kurnik
    Dr. v. Haunersches Kinderspital, University of Munich, Munich, Germany;
  • Ri Liesner
    Hemophilia Center, Department of Haematology, Great Ormond Street Hospital for children, London, UK;
  • Pia Petrini
    Department of Pediatrics, Clinic of Coagulation Disorders, Karolinska Hospital, Stockholm, Sweden;
  • Helen Platokouki
    St. Sophia Children’s Hospital, Haemophilia-Haemostasis Unit, Athens, Greece;
  • Carmen Altisent
    Unitat Hemofilia, Hospital Traumatologica, Hospital Vall d’Hebron, Barcelona, Spain;
  • Johannes Oldenburg
    Institut für Experimentelle Hämatologie und Transfusionsmedizin, Universitätsklinikum Bonn, Bonn, Germany;
  • Beatrice Nolan
    Department of Paediatric Haematology, St. James's Hospital, Dublin, Ireland;
  • Rosario Pérez Garrido
    Hospital General Unidad de Hemofilia, Hospitales Universitarios Virgen del Rocio, Sevilla, Spain;
  • M. Elisa Mancuso
    Angelo Bianchi Bonomi Hemophilia and Thrombosis Center, Fondazione Istituto di Ricovero e Cura a Carattere Scientifico Ca’ Granda, Ospedale Maggiore Policlinico, Milan, Italy;
  • Anne Rafowicz
    Centre Régional de Traitement de l'Hémophilie et Autres Maladies Bicetre, Service Hématologique, Paris, France;
  • Mike Williams
    Department of Haematology, The Children’s Hospital, Birmingham, UK;
  • Niels Clausen
    Department of Pediatrics, University Hospital of Aarhus at Skejby, Aarhus, Denmark;
  • Rutger A. Middelburg
    Center for Clinical Transfusion Research, Sanquin Foundation, Leiden, The Netherlands;
  • Rolf Ljung
    Department of Pediatrics and Malmö Centre for Thrombosis and Haemostasis, Skånes Universitetssjukhus, Malmö, Sweden; and
  • Johanna G. van der Bom
    Center for Clinical Transfusion Research, Sanquin Foundation, Leiden, The Netherlands;

書誌事項

公開日
2013-05-16
DOI
  • 10.1182/blood-2012-09-457036
公開者
American Society of Hematology

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説明

<jats:title>Key Points</jats:title> <jats:p>High-dose intensive factor VIII treatment increases the risk for inhibitor development in patients with severe hemophilia A. In patients with severe hemophilia A, factor VIII prophylaxis decreases inhibitor risk, especially in patients with low-risk F8 mutations.</jats:p>

収録刊行物

  • Blood

    Blood 121 (20), 4046-4055, 2013-05-16

    American Society of Hematology

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