Atlanto-axial rotatory fixation following pharyngeal flap plasty in a patient with 22q11 deletion syndrome

  • MUKAI Takao
    Department of Oral and Maxillofacial Surgery, Osaka Medical Center and Research Institute for Maternal and Child Health
  • YAMANISHI Tadashi
    Division of Pathogenesis and Control of Oral Diseases, Graduate School of Dentistry, Osaka University
  • YOKOTA Yusuke
    Department of Oral and Maxillofacial Surgery, Osaka Medical Center and Research Institute for Maternal and Child Health
  • HIRANO Yoshiko
    Department of Oral and Maxillofacial Surgery, Osaka Medical Center and Research Institute for Maternal and Child Health
  • NISHIO Juntaro
    Department of Oral and Maxillofacial Surgery, Osaka Medical Center and Research Institute for Maternal and Child Health

Bibliographic Information

Other Title
  • 咽頭弁形成術後に環軸椎回旋位固定を生じた22q11欠失症候群患者の1例
  • ショウレイ ホウコク イントウベン ケイセイ ジュツゴ ニ カンジクツイ カイセンイ コテイ オ ショウジタ 22q11 ケツシツショウコウグン カンジャ ノ 1レイ

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Abstract

We describe an 8-year girl with atlanto-axial rotatory fixation (AARF) caused accidentally after pharyngeal flap plasty under general anesthesia. On the third postoperative day, she had torticollis without neurologic damage and complained of neck pain when she rotated her head. AARF was diagnosed on the basis of the computed tomographic findings. Glisson traction with 1.5 kilograms of weight for 2 weeks reduced the dislocation, but further treatment was reguired. The deformity was corrected by manipulation under general anesthesia and the patient's head and neck were immoblilized in a Minerva jacket for 6 weeks. A cervical collar was used subsequently in an attempt to maintain normal spinal alignment, and the reduction remained.<BR>AARF is a rare disorder caused by a variety of conditions. Diagnosis is often difficult and delayed. During operation, hyperextension of the neck should be avoided. It is important to be aware of AARF and to begin treatment as soon as possible in patients with postoperative manifestations such as head tilt, neck pain, and inability to rotate the head.

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