One case report of angiolymphoid hyperplasia with eosinophilia (ALHE) of the parotid gland with a preoperative diagnosis of aneurysms

DOI
  • HONGO Takahiro
    Department of Otorhinolaryngology, KKR Hamanomachi General Hospital Department of Otorhinolaryngology, Graduate School of Medical Sciences, Kyushu University
  • SAWATSUBASHI Motohiro
    Department of Otorhinolaryngology, Graduate School of Medical Sciences, Kyushu University
  • NISHIJIMA Toshimitsu
    Department of Otorhinolaryngology, Graduate School of Medical Sciences, Kyushu University Department of Anatomic Pathology, Graduate School of Medical Sciences, Kyushu University
  • YAMAMOTO Hidetaka
    Department of Anatomic Pathology, Graduate School of Medical Sciences, Kyushu University
  • NAKASHIMA Torahiko
    Department of Otorhinolaryngology, Graduate School of Medical Sciences, Kyushu University

Bibliographic Information

Other Title
  • 術前に動脈瘤が疑われた耳下腺類上皮血管腫 （Angiolymphoid hyperplasia with eosinophilia：ALHE） の 1 例

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Abstract

<p>Angiolymphoid hyperplasia with eosinophilia (ALHE) is a rare idiopathic condition that manifests in adults as deep-red papules and nodules in the skin of the head and neck. We herein present the case of a 29-year-old man who was admitted with a pulsatile parotid tumor. A CT scan showed that an expanded small blood vessel carried through the tumor was enhanced at the same level of the blood vessel. MRA showed that a branch of the superficial temporal artery flowed into the tumor. According to these findings, the preoperative diagnosis was an aneurysm. In the intraoperative findings, the tumor was located in the deep lobe and a blood vessel flowed into the tumor. The tumor was composed of a proliferation of thick or thin-walled blood vessels lined by plump epithelioid endothelial cells, accompanied by fibrous stroma and infiltration of eosinophils. Immunohistochemically, these plump endothelial cells were positive for CD31 and CD34. Therefore, the postoperative diagnosis was ALHE. We herein review the current understanding of ALHE and discuss how to differentiate it from Kimura's disease.</p>

Journal

  • jibi to rinsho

    jibi to rinsho 62 (2), 63-72, 2016-03-20

    JIBI TO RINSHO KAI

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