A Case Report of Lung Resection in a Boy With Bilateral Swyer-James Syndrome Due to Multiple Cysts in the Left Upper Lobe and Complete Atelectasis in the Left Lower Lobe

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  • Yamada Takaharu
    Department of Pediatric Surgery, Ehime University Hospital Department of Pediatric Surgery, Saga University Hospital
  • Shibui Yuichi
    Department of Pediatric Surgery, Ehime University Hospital Department of Pediatric Surgery, Graduate School of Medical Science, Kyushu University
  • Watanabe Yuji
    Department of Gastrointestinal Surgery and Surgical Oncology, Postgraduate School of Medicine, Ehime University

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Other Title
  • 左上葉多発囊胞および左下葉無気肺に対して肺切除を施行した両側Swyer-James症候群の1男児例
  • 症例報告 左上葉多発囊胞および左下葉無気肺に対して肺切除を施行した両側Swyer-James症候群の1男児例
  • ショウレイ ホウコク ヒダリウエ ヨウ タハツノウホウ オヨビ ヒダリシタ ヨウ ムキハイ ニ タイシテ ハイ セツジョ オ シコウ シタ リョウガワ Swyer-James ショウコウグン ノ 1 ダンジレイ

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<p>Swyer-James syndrome (SJS) is a rare condition characterized by increased permeability of one pulmonary or lung lobe and loss of pulmonary blood vessel shadow in chest X-ray. Recently, the number of case reports of bilateral or patchy lesions have been increasing owing to the development of computed tomography (CT). We encountered a case of bilateral SJS in a 7-year-old boy and performed thoracoscopy-assisted pulmonary resection. The boy, who had histories of repeated pneumonia, bronchitis, asthma, and infection of a left apical lung cyst, was referred to our hospital. Chest CT showed lobar emphysema with multiple cysts in the left upper lobe and complete atelectasis in the left lower lobe, as well as whole expansion and patchy emphysema in the right lung, in addition to obstruction of the peripheral bronchus in the left upper lobe and narrowing of the left pulmonary vessels. Therefore, we diagnosed him as having SJS. We performed thoracoscopy-assisted partial resection of the left upper lobe and left lower lobectomy, considering ventilation failure due to recurrent cyst infection or shunt blood flow in complete atelectasis. He was discharged on the 15th postoperative day, and no rehospitalization due to respiratory tract infection or asthma attack occurred until 10 months after surgery. We should consider SJS in cases of repeated respiratory infections from the infantile period, and then consider lung resection if a patient suffers from infectious cyst formation or respiratory distress, even in childhood.</p>

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